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IEMbase 0720: COA5-related cytochrome c oxidase assembly factor 5 deficiency

Scope

Field Value
IEMbase ID 720
Nosology 7.4.16.01
Nosology code IEM1147
Gene COA5
External IDs OMIM:616500; ORPHA:1561
Generated mapping CANDIDATE to COX15-Related_COX_Deficiency.yaml
Candidate DisMech targets No exact COA5 target identified
Review date 2026-07-07

IEMbase phenotype signal

IEMbase represents autosomal recessive COA5-related cytochrome c oxidase assembly factor 5 deficiency. The alternate-name field links the record to fatal infantile cardioencephalomyopathy due to cytochrome c oxidase deficiency 3.

The cached phenotype signal is sparse but severe: neonatal cardiomyopathy and neonatal perinatal death.

DisMech phenotype coverage

No exact COA5 local target was identified.

The generated COX15-Related_COX_Deficiency.yaml candidate is related at the broad complex IV/COX-deficiency level, but it is a COX15 heme A synthase disorder and corresponds to fatal infantile cardioencephalomyopathy due to cytochrome c oxidase deficiency 2. It is not the COA5/type 3 disease.

Concordance and completeness

Judgement: true local COA5 gap. The COX15 candidate should be rejected as exact coverage.

Both records sit in the severe complex IV cardioencephalomyopathy space, but the gene and named disease type differ. Mapping COA5 to COX15 would collapse distinct COX-deficiency subtypes.

Curation actions

  • Add a dedicated COA5 complex IV/COX assembly deficiency target if curated.
  • Reject COX15-Related_COX_Deficiency.yaml as exact COA5 coverage.
  • Preserve neonatal cardiomyopathy and perinatal death.
  • Keep COA5 fatal infantile COX deficiency type 3 separate from COX15/type 2.