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IEMbase 0493: PGAM2-related muscle phosphoglycerate mutase deficiency

Scope

Field Value
IEMbase ID 493
Nosology 3.3.11.01
Gene PGAM2
External IDs OMIM:261670; ORPHA:97234
Generated mapping CANDIDATE; MEDIUM; Glycogen_Storage_Disease_Type_I.yaml
Candidate DisMech targets Glycogen_Storage_Disease_Type_I.yaml
Review date 2026-07-07

IEMbase phenotype signal

IEMbase represents autosomal recessive PGAM2-related muscle phosphoglycerate mutase deficiency as glycogen storage disease type X / DiMauro disease. No treatments are listed. Biochemical rows include increased plasma creatine kinase, decreased muscle phosphoglycerate mutase, normal-to-increased muscle glycogen, and increased urine myoglobin. No clinical rows are listed in the local JSON.

DisMech phenotype coverage

Glycogen_Storage_Disease_Type_I.yaml is not the correct target. It covers G6PC1/SLC37A4 glucose-6-phosphatase system deficiency and hepatic/renal fasting-hypoglycemia biology. It does not model PGAM2, muscle phosphoglycerate mutase deficiency, GSD X, DiMauro disease, exercise-induced myoglobinuria, or the skeletal-muscle glycolysis block implied by the IEMbase record.

Concordance and completeness

Judgement: false-positive candidate; true PGAM2/GSD X local gap.

The generated candidate shares only broad glycogen-storage vocabulary. IEMbase's disease is a skeletal-muscle glycolytic enzyme deficiency with CK and myoglobinuria markers, not a hepatic glucose-6-phosphatase disorder. Local Glycogen_Storage_Disease_Type_VII.yaml provides related glycolytic myopathy context, but it is PFKM/Tarui disease and should not be treated as exact PGAM2 coverage.

Curation actions

  • Do not map this record to Glycogen_Storage_Disease_Type_I.yaml.
  • Track PGAM2-related GSD X / DiMauro disease as a local curation gap.
  • Preserve IEMbase prompts for muscle phosphoglycerate mutase activity, creatine kinase, muscle glycogen, and urine myoglobin for a future exact entry.