โš™

Pathophysiology Nodes

5
5 shared nodes are defined in this module.
โ—‰

Cell Types

3
radial glial cell CL:0000681 pyramidal neuron CL:0000598 migrating cortical neuron CL:0000540
โ‡„

Biological Processes

5
PI3K-AKT Signal Transduction GO:0043491 INCREASED TOR Signaling GO:0031929 INCREASED Neural Progenitor Proliferation GO:0008283 INCREASED Cerebral Cortex Development GO:0021987 ABNORMAL Neuronal Migration GO:0001764 ABNORMAL
i

Notes

This is a mechanism module, not a specific disease. Disorder entries reference individual nodes via conforms_to (e.g., "pi3k_akt_mtor_cortical_overgrowth#PI3K-AKT-mTOR Pathway Hyperactivation in Neural Progenitors"). Conforming nodes should substitute the disorder-specific activating lesion: somatic mosaic PIK3CA (hemimegalencephaly, CLOVES/PROS), germline or postzygotic PIK3R2 or AKT3 (MCAP/MPPH megalencephaly spectrum), brain somatic MTOR (focal cortical dysplasia type II), or CCND2 stabilization (MPPH). Existing dismech entries CLOVES_Syndrome.yaml and Tuberous_Sclerosis_Complex.yaml model upstream/parallel arms of this pathway and could add conforms_to references to the "PI3K-AKT-mTOR Pathway Hyperactivation in Neural Progenitors" node; TSC reaches the same mTORC1 hyperactivation node through TSC1/TSC2 loss rather than a PI3K-activating variant. A non-cell-autonomous AKT3-FOXG1-Reelin branch (restricted AKT3-mutant progenitors misexpressing Reelin and misrouting neighboring wild-type neurons; Romero et al. 2018 review sections 2.2.1.8/2.2.8) is a candidate additional node shared with the Reelin lamination module (epic #4098), but is deferred here pending verification of its primary sources and is intentionally not asserted without quotable primary-paper evidence.
โ†—

Used By Disorder Entries

0
No disorder entries currently reference this module via conforms_to.
โฌก

Pathograph

Use the checkboxes to hide or show graph categories. Hover nodes for evidence-backed metadata.
Pathograph: causal mechanism network for PI3K-AKT-mTOR Cortical Overgrowth Module Interactive directed graph showing how this shared module's pathophysiology nodes connect.
โš™

Pathophysiology

5
PI3K-AKT-mTOR Pathway Hyperactivation in Neural Progenitors
trigger
The conserved initiating lesion is constitutive activation of the PI3K-AKT-mTOR growth-signaling cascade in neural progenitor cells. Activating variants in three core components of the PI3K-AKT pathway - PIK3CA (p110-alpha catalytic subunit), PIK3R2 (p85-beta regulatory subunit), and AKT3 - or in the downstream kinase MTOR drive ligand-independent signaling. These variants are frequently post-zygotic somatic (mosaic) events confined to the developing brain, producing mosaic hyperactivation in a clone of progenitors and their progeny.
radial glial cell CL:0000681
PI3K-AKT Signal Transduction GO:0043491 INCREASED TOR Signaling GO:0031929 INCREASED
Progenitor Hyperproliferation and Cell-Cycle Dysregulation
amplifier
Hyperactive PI3K-AKT-mTOR signaling increases biosynthesis, cell growth, and proliferation of neural progenitors while dysregulating cell-cycle control. Stabilization of cyclin D2 (CCND2) - normally targeted for proteasomal degradation downstream of GSK-3-beta, which is inhibited by AKT - links the pathway to G1/S cell-cycle progression and expands the progenitor pool, increasing the neuronal output that is subsequently malpositioned.
radial glial cell CL:0000681
Neural Progenitor Proliferation GO:0008283 INCREASED
Cortical Overgrowth
effector
Progenitor hyperproliferation and increased cell growth enlarge the cortex, producing megalencephaly when diffuse and hemimegalencephaly when the activating mosaic clone is confined to one hemisphere. The degree and distribution of overgrowth track the timing and spatial extent of the somatic-mosaic activating event.
pyramidal neuron CL:0000598
Cerebral Cortex Development GO:0021987 ABNORMAL
Impaired Neuronal Migration and Cortical Lamination
effector
Beyond overgrowth, PI3K-AKT-mTOR hyperactivation perturbs radial neuronal migration and inside-out cortical lamination, yielding dyslamination and a polymicrogyria-like or focal cortical dysplasia cortical architecture. The migration defect is mechanistically separable from the proliferative overgrowth and contributes the malformed (as opposed to merely enlarged) component of the phenotype.
migrating cortical neuron CL:0000540
Neuronal Migration GO:0001764 ABNORMAL
Epileptogenic Cortical Dysplasia and Seizures
outcome
The overgrown, dyslaminated cortex containing cytomegalic dysmorphic neurons (and, in focal cortical dysplasia type II, balloon cells) forms an epileptogenic substrate that generates medically refractory seizures. Persistent mTOR hyperactivation in these abnormal neurons shifts the cortical network toward excitation, and the seizures are frequently intractable to antiseizure medication but responsive to mTOR inhibition, identifying the pathway as a treatment target. This terminal step conforms to the conserved epilepsy excitation-inhibition imbalance module, with the mTOR-pathway cortical malformation as the disorder-specific driver of the imbalance.
dysmorphic cytomegalic neuron CL:0000540
TOR Signaling GO:0031929 INCREASED