Pathophysiology Nodes

5
5 shared nodes are defined in this module.

Cell Types

2
keratinocyte CL:0000312 Cell Ontology (CL) Relation: this mechanism module involves this cell type This mechanism module involves keratinocyte (CL:0000312). CL:0000312 is a cell type from the Cell Ontology. corneocyte CL:0002153 Cell Ontology (CL) Relation: this mechanism module involves this cell type This mechanism module involves corneocyte (CL:0002153). CL:0002153 is a cell type from the Cell Ontology.

Biological Processes

8
keratinocyte differentiation GO:0030216 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves decreased keratinocyte differentiation (GO:0030216). GO:0030216 is a biological process from the Gene Ontology. DECREASED transglutaminase-mediated peptide cross-linking GO:0018149 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves decreased transglutaminase-mediated peptide cross-linking (GO:0018149). GO:0018149 is a biological process from the Gene Ontology. DECREASED cornified envelope assembly GO:1903575 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves decreased cornified envelope assembly (GO:1903575). GO:1903575 is a biological process from the Gene Ontology. DECREASED lamellar body lipid transport GO:0006869 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves decreased lamellar body lipid transport (GO:0006869). GO:0006869 is a biological process from the Gene Ontology. DECREASED establishment of skin barrier GO:0061436 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves decreased establishment of skin barrier (GO:0061436). GO:0061436 is a biological process from the Gene Ontology. DECREASED keratinocyte proliferation GO:0043616 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves increased keratinocyte proliferation (GO:0043616). GO:0043616 is a biological process from the Gene Ontology. INCREASED keratinization GO:0031424 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves increased keratinization (GO:0031424). GO:0031424 is a biological process from the Gene Ontology. INCREASED epidermis development GO:0008544 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves abnormal epidermis development (GO:0008544). GO:0008544 is a biological process from the Gene Ontology. ABNORMAL
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Notes

This is a shared mechanism module, not a disease. Disorder-specific substitutions at the trigger node: TGM1 (transglutaminase-1 cross-linking of the protein envelope), FLG (profilaggrin-derived keratin aggregation matrix), ALOX12B / ALOXE3 (the epidermal lipoxygenase pathway acting on the corneocyte lipid envelope), ABCA12 (lamellar-body glucosylceramide transporter), STS (steroid sulfatase; cholesterol sulfate accumulation), SPINK5 (LEKTI restraint of kallikrein-mediated desquamation), ALDH3A2 (Sjogren-Larsson fatty aldehyde dehydrogenase), ABHD5/PNPLA2 (Chanarin-Dorfman neutral lipid storage), and the distal cholesterol biosynthetic enzymes (CHILD/CDPX2/MSMO1 group). Deliberately scoped to the cornification arm. Three related mechanisms are NOT re-derived here and have their own modules: dominant-negative keratin filament collapse (`keratin_intermediate_filament_fragility`, which the epidermolytic ichthyoses conform to *in parallel* with this module), desmosomal adhesion loss (`desmosomal_adhesion_failure`), and the type 2 allergic-sensitization arm of barrier loss (`epithelial_barrier_dysfunction`, which models where barrier failure leads *immunologically* rather than how cornification fails structurally). A filaggrin-deficient entry may reasonably conform to both this module and `epithelial_barrier_dysfunction`. Not an Xogenesis module: the terminal output is the failure of a normal programmed process (cornification), not the formation of a new pathological anatomical entity. Barrier failure is the intended conformance target because it is the node every route funnels through and the node topical therapy acts on. Attaching at the trigger node alone is insufficient for conformance - an entry must evidence the barrier consequence, not merely a mutation in a cornification gene.

Used By Disorder Entries

7

Pathograph

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Pathograph: causal mechanism network for Epidermal Cornification Failure Module Interactive directed graph showing how this shared module's pathophysiology nodes connect.

Pathophysiology

5
Cornification Program Component Deficiency
trigger
A structural, enzymatic, or lipid-transport component required for terminal keratinocyte differentiation is deficient or absent. The affected component differs by disorder, but each is required for the orderly conversion of a granular-layer keratinocyte into a corneocyte.
keratinocyte CL:0000312 Cell Ontology (CL) Relation: this pathophysiological event involves this cell type This pathophysiological event involves keratinocyte (CL:0000312). CL:0000312 is a cell type from the Cell Ontology.
keratinocyte differentiation GO:0030216 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves decreased keratinocyte differentiation (GO:0030216). GO:0030216 is a biological process from the Gene Ontology. DECREASED transglutaminase-mediated peptide cross-linking GO:0018149 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves decreased transglutaminase-mediated peptide cross-linking, annotated with peptide cross-linking (GO:0018149). GO:0018149 is a biological process from the Gene Ontology. DECREASED
Defective Cornified Envelope Assembly and Lamellar Lipid Delivery
amplifier
The two structural arms of cornification fail. The insoluble, transglutaminase cross-linked protein envelope beneath the corneocyte plasma membrane is incompletely assembled, and/or lamellar bodies fail to deliver glucosylceramides and other lipid precursors to the extracellular space, so the intercellular lipid lamellar membrane of the stratum corneum is not formed. Either arm alone is sufficient to compromise the barrier; most disorders show some degree of both.
keratinocyte CL:0000312 Cell Ontology (CL) Relation: this pathophysiological event involves this cell type This pathophysiological event involves keratinocyte (CL:0000312). CL:0000312 is a cell type from the Cell Ontology. corneocyte CL:0002153 Cell Ontology (CL) Relation: this pathophysiological event involves this cell type This pathophysiological event involves corneocyte (CL:0002153). CL:0002153 is a cell type from the Cell Ontology.
cornified envelope assembly GO:1903575 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves decreased cornified envelope assembly (GO:1903575). GO:1903575 is a biological process from the Gene Ontology. DECREASED lamellar body lipid transport GO:0006869 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves decreased lamellar body lipid transport, annotated with lipid transport (GO:0006869). GO:0006869 is a biological process from the Gene Ontology. DECREASED
epidermal lamellar body GO:0097209 Gene Ontology (GO) Relation: this pathophysiological event involves this cellular component This pathophysiological event involves epidermal lamellar body (GO:0097209). GO:0097209 is a cellular component from the Gene Ontology.
Stratum Corneum Permeability Barrier Failure
central effector
The stratum corneum fails as a permeability barrier: transepidermal water loss rises and the epidermis is more permeable to the external environment. This is the rate-limiting, disorder-agnostic node of the module - every upstream route converges here, and it is the node topical barrier-repair therapy targets.
corneocyte CL:0002153 Cell Ontology (CL) Relation: this pathophysiological event involves this cell type This pathophysiological event involves corneocyte (CL:0002153). CL:0002153 is a cell type from the Cell Ontology.
establishment of skin barrier GO:0061436 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves decreased establishment of skin barrier (GO:0061436). GO:0061436 is a biological process from the Gene Ontology. DECREASED
Compensatory Epidermal Hyperproliferation and Retention Hyperkeratosis
effector
Two processes thicken the stratum corneum. First, barrier disruption stimulates epidermal DNA synthesis and hyperplasia as a homeostatic attempt to restore the barrier. Second, corneocyte shedding is impaired, so corneocytes are retained rather than desquamated. Disorders differ in which process dominates - retention hyperkeratosis is the primary mechanism in X-linked ichthyosis, whereas hyperproliferative kinetics predominate in the congenital ichthyosiform erythrodermas.
keratinocyte CL:0000312 Cell Ontology (CL) Relation: this pathophysiological event involves this cell type This pathophysiological event involves keratinocyte (CL:0000312). CL:0000312 is a cell type from the Cell Ontology.
keratinocyte proliferation GO:0043616 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves increased keratinocyte proliferation (GO:0043616). GO:0043616 is a biological process from the Gene Ontology. INCREASED keratinization GO:0031424 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves increased keratinization (GO:0031424). GO:0031424 is a biological process from the Gene Ontology. INCREASED
Ichthyotic Scaling and Cutaneous Barrier Complications
consequence
The clinical endpoint: generalized adherent scaling, with disorder-dependent erythroderma, palmoplantar keratoderma, and fissuring. Because the defect is a permeability barrier defect and not merely a cosmetic one, severe forms carry neonatal transcutaneous water and electrolyte loss, impaired thermoregulation, and increased cutaneous infection risk.
epidermis development GO:0008544 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves abnormal epidermis development (GO:0008544). GO:0008544 is a biological process from the Gene Ontology. ABNORMAL