Pathophysiology Nodes

5
5 shared nodes are defined in this module.

Cell Types

2
basal keratinocyte CL:0002187 Cell Ontology (CL) Relation: this mechanism module involves this cell type This mechanism module involves basal keratinocyte (CL:0002187). CL:0002187 is a cell type from the Cell Ontology. skin fibroblast CL:0002620 Cell Ontology (CL) Relation: this mechanism module involves this cell type This mechanism module involves skin fibroblast (CL:0002620). CL:0002620 is a cell type from the Cell Ontology.

Biological Processes

7
hemidesmosome assembly GO:0031581 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves decreased hemidesmosome assembly (GO:0031581). GO:0031581 is a biological process from the Gene Ontology. DECREASED cell-matrix adhesion GO:0007160 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves decreased cell-matrix adhesion (GO:0007160). GO:0007160 is a biological process from the Gene Ontology. DECREASED cell-substrate adhesion GO:0031589 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves decreased cell-substrate adhesion (GO:0031589). GO:0031589 is a biological process from the Gene Ontology. DECREASED cell adhesion GO:0007155 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves decreased cell adhesion (GO:0007155). GO:0007155 is a biological process from the Gene Ontology. DECREASED wound healing GO:0042060 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves abnormal wound healing (GO:0042060). GO:0042060 is a biological process from the Gene Ontology. ABNORMAL extracellular matrix organization GO:0030198 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves abnormal extracellular matrix organization (GO:0030198). GO:0030198 is a biological process from the Gene Ontology. ABNORMAL epidermis development GO:0008544 Gene Ontology (GO) Relation: this mechanism module involves this biological process This mechanism module involves abnormal epidermis development (GO:0008544). GO:0008544 is a biological process from the Gene Ontology. ABNORMAL
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Notes

This is a shared mechanism module, not a disease. Disorder-specific substitutions at the trigger node, ordered by the cleavage plane each produces: PLEC (the plectin link from the keratin network into the hemidesmosome); ITGA6 / ITGB4 and COL17A1 (hemidesmosomal); LAMA3 / LAMB3 / LAMC2 (lamina lucida, the anchoring filament level); COL7A1 (sublamina densa, the anchoring fibril level); FERMT1 / kindlin-1 (mixed, and the reason Kindler EB shows more than one plane in the same biopsy). KRT5 and KRT14 are deliberately NOT in that list even though they cause an EB subtype, because they are intracellular filament proteins rather than components of the extracellular attachment network this node asserts. See the scope boundary below. Scope boundary with `keratin_intermediate_filament_fragility`. Epidermolysis bullosa simplex is classified as EB because it blisters, but its proximal lesion is dominant-negative collapse of the keratin network inside the basal keratinocyte, not loss of an extracellular attachment component. An EBS entry should conform to the keratin module, and should NOT conform to this module's trigger node. It should not conform to this module's *separation* node either, and the reason is worth stating because it is easy to get wrong: EBS splits **intraepidermally**, through the cytolysing basal keratinocyte, above an intact basement membrane zone - not at the dermal-epidermal junction. The blister looks the same clinically and the plane is not the same. What EBS shares with this module is the keratin module's cytolysis node, which is where its separation belongs. PLEC (plectin) is the genuine hinge and the one EBS-associated gene that does belong here, because plectin is a hemidesmosomal component linking the keratin network into the attachment complex; a plectin-deficient entry has a real claim on both this module's trigger and the keratin module's. This module models the *inherited* attachment defect. The acquired autoantibody-mediated route to the same cleavage planes (epidermolysis bullosa acquisita, bullous pemphigoid, anti-laminin-332 mucous membrane pemphigoid) reaches the separation node through immune targeting of the same proteins; such an entry may conform at the separation node while curating its own autoimmune trigger. Not an Xogenesis module: the blister is a plane of tissue separation - a failure of an adhesive structure - not the formation of a new pathological anatomical entity. Conformance requires evidence of mechanically-provoked separation at the dermal-epidermal junction. A gene expressed at the basement membrane zone, or a disorder with skin fragility from a different cause (cornification defects, desmosomal acantholysis), does not conform on that basis alone.

Used By Disorder Entries

6

Pathograph

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Pathograph: causal mechanism network for Dermal-Epidermal Junction Adhesion Failure Module Interactive directed graph showing how this shared module's pathophysiology nodes connect.

Pathophysiology

5
Basement Membrane Zone Attachment Component Defect
trigger
A structural component of the interconnected hemidesmosome - anchoring filament - anchoring fibril network of the cutaneous basement membrane zone is absent, reduced, or structurally abnormal. The network spans from the keratin cytoskeleton of the basal keratinocyte, across the lamina lucida and lamina densa, into the papillary dermis, and each disorder removes one link from it.
basal keratinocyte CL:0002187 Cell Ontology (CL) Relation: this pathophysiological event involves this cell type This pathophysiological event involves basal keratinocyte, annotated with basal cell of epidermis (CL:0002187). CL:0002187 is a cell type from the Cell Ontology.
hemidesmosome assembly GO:0031581 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves decreased hemidesmosome assembly (GO:0031581). GO:0031581 is a biological process from the Gene Ontology. DECREASED cell-matrix adhesion GO:0007160 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves decreased cell-matrix adhesion (GO:0007160). GO:0007160 is a biological process from the Gene Ontology. DECREASED
cutaneous basement membrane GO:0005604 Gene Ontology (GO) Relation: this pathophysiological event involves this cellular component This pathophysiological event involves cutaneous basement membrane, annotated with basement membrane (GO:0005604). GO:0005604 is a cellular component from the Gene Ontology.
Loss of Adhesive Integrity at a Defined Cleavage Plane
amplifier
The attachment network loses tensile competence at one specific ultrastructural level - within the basal keratinocyte, at the hemidesmosome, within the lamina lucida, or beneath the lamina densa - determined by where the missing component sits. This level-specificity is the organizing principle of EB classification: the same clinical sign (a blister) arising at different depths defines the simplex, junctional, and dystrophic categories, and predicts whether healing will be scarless or scarring.
basal keratinocyte CL:0002187 Cell Ontology (CL) Relation: this pathophysiological event involves this cell type This pathophysiological event involves basal keratinocyte, annotated with basal cell of epidermis (CL:0002187). CL:0002187 is a cell type from the Cell Ontology.
cell-substrate adhesion GO:0031589 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves decreased cell-substrate adhesion (GO:0031589). GO:0031589 is a biological process from the Gene Ontology. DECREASED
Mechanically Induced Dermal-Epidermal Separation and Blistering
central effector
Ordinary mechanical shear - friction, pressure, minor trauma - separates the tissue at the incompetent plane, and fluid accumulates in the resulting cleft to form a blister or erosion. This is the rate-limiting, disorder-agnostic node of the module: every attachment-component lesion converges here, and it is the node against which conformance should be declared.
basal keratinocyte CL:0002187 Cell Ontology (CL) Relation: this pathophysiological event involves this cell type This pathophysiological event involves basal keratinocyte, annotated with basal cell of epidermis (CL:0002187). CL:0002187 is a cell type from the Cell Ontology.
cell adhesion GO:0007155 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves decreased cell adhesion (GO:0007155). GO:0007155 is a biological process from the Gene Ontology. DECREASED
Chronic Erosion, Impaired Healing and Dermal Scarring
effector
Ruptured blisters leave chronic, slowly healing erosions and wounds. Where the plane of separation lies beneath the lamina densa, healing is fibrotic rather than restitutive, producing milia, atrophic scarring, and progressive contracture. The persistently wounded, inflamed, and fibrotic dermal microenvironment is itself the substrate for the malignant complication. Forms that split above the lamina densa heal without scarring, so this node is reached to markedly different degrees across conforming disorders.
skin fibroblast CL:0002620 Cell Ontology (CL) Relation: this pathophysiological event involves this cell type This pathophysiological event involves skin fibroblast (CL:0002620). CL:0002620 is a cell type from the Cell Ontology.
wound healing GO:0042060 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves abnormal wound healing (GO:0042060). GO:0042060 is a biological process from the Gene Ontology. ABNORMAL extracellular matrix organization GO:0030198 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves abnormal extracellular matrix organization (GO:0030198). GO:0030198 is a biological process from the Gene Ontology. ABNORMAL
Cutaneous and Extracutaneous Complications of Skin Fragility
consequence
The organ-level endpoint. Because the same attachment network operates in every stratified squamous epithelium, fragility is not confined to skin: nail dystrophy, oral and oesophageal erosion with stricture, corneal erosion, and dental enamel defects occur depending on which component is lost. In the sublamina densa forms, cutaneous squamous cell carcinoma arising in chronically wounded skin becomes the leading cause of death in adulthood, and it is not UV-driven.
epidermis development GO:0008544 Gene Ontology (GO) Relation: this pathophysiological event involves this biological process This pathophysiological event involves abnormal epidermis development (GO:0008544). GO:0008544 is a biological process from the Gene Ontology. ABNORMAL