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1
Inheritance
4
Pathophys.
4
Phenotypes
4
Pathograph
🏷

Classifications

👪

Inheritance

1
Autosomal recessive inheritance HP:0000007
Autosomal recessive inheritance
Show evidence (1 reference)
PMID:39079473 SUPPORT Human Clinical
"Acatalasemia is a very rare disorder characterized by gangrenous oral ulcerations and is caused by biallelic variants in the CAT gene"
Supports biallelic CAT variants and the recessive disease model.

Pathophysiology

4
CAT Catalase Deficiency
Biallelic CAT variants reduce catalase enzyme activity, impairing the conversion of hydrogen peroxide to water and oxygen.
CAT hgnc:1516
hydrogen peroxide catabolic process GO:0042744 ↓ DECREASED
catalase activity GO:0004096 ↓ DECREASED
peroxisome GO:0005777
Show evidence (2 references)
PMID:39079473 SUPPORT Human Clinical
"biallelic variants in the CAT gene which encodes the catalase enzyme that decomposes the hydrogen peroxide molecules to remove their toxic effect."
Supports CAT variants and catalase-mediated hydrogen peroxide decomposition.
PMID:1999334 SUPPORT Other
"in the acatalasemic gene causes a splicing mutation and hence a deficiency of mRNA."
Historical molecular review supports catalase gene defects as the cause of acatalasemia.
Impaired Hydrogen Peroxide Detoxification
Catalase deficiency leaves hydrogen peroxide less efficiently decomposed, increasing the oxidant burden on oral tissues, blood, and metabolically active tissues.
hydrogen peroxide catabolic process GO:0042744 ↓ DECREASED response to oxidative stress GO:0006979 ↑ INCREASED
Show evidence (2 references)
PMID:22365890 SUPPORT Other
"The enzyme catalase catalyzes the breakdown of hydrogen peroxide into oxygen and water. It is the main regulator of hydrogen peroxide metabolism."
Supports the hydrogen peroxide detoxification role of catalase.
PMID:22365890 SUPPORT Other
"Excessive concentrations may cause significant damages to protein, DNA, RNA and lipids."
Supports oxidative macromolecular damage as the consequence of excess hydrogen peroxide.
Gangrenous Oral and Periodontal Tissue Injury
Acatalasia can manifest as gangrenous oral ulcerations and periodontitis, with loose dentition and premature tooth loss in affected individuals.
gingival epithelial cell CL:0002621
Show evidence (2 references)
PMID:39079473 SUPPORT Human Clinical
"Acatalasemia is a very rare disorder characterized by gangrenous oral ulcerations"
Supports gangrenous oral ulcerations as a core manifestation.
PMID:39079473 SUPPORT Human Clinical
"two siblings from a consanguineous Egyptian family presenting with joint hyperlaxity, loose dentitions with gangrenous periodontitis, and early loss of teeth."
Supports periodontal injury and tooth loss in recent affected siblings.
Diabetes Mellitus Susceptibility
Reviews of acatalasemia and diabetes propose that inherited catalase deficiency can increase type 2 diabetes risk, especially in females, through chronic hydrogen peroxide and oxidative stress.
Show evidence (1 reference)
PMID:22365890 SUPPORT Other
"Inherited catalase deficiency may increase the risk of type 2 diabetes mellitus, especially for females."
Supports type 2 diabetes susceptibility as an associated downstream phenotype.

Pathograph

Use the checkboxes to hide or show graph categories. Hover nodes for evidence and cross-linked metadata.
Pathograph: causal mechanism network for Acatalasia Interactive directed graph showing how pathophysiology mechanisms, phenotypes, genetic factors and variants, experimental models, environmental triggers, and treatments relate through causal and linked edges.

Phenotypes

4
Head and Neck 2
Gangrenous oral ulcerations Oral ulcer HP:0000155
Show evidence (1 reference)
PMID:39079473 SUPPORT Human Clinical
"Acatalasemia is a very rare disorder characterized by gangrenous oral ulcerations"
Supports oral ulcerations in acatalasia.
Abnormality of the gingiva Abnormality of the gingiva HP:0000168
Show evidence (1 reference)
PMID:39079473 SUPPORT Human Clinical
"loose dentitions with gangrenous periodontitis"
Supports gingival/periodontal involvement.
Other 2
Premature loss of teeth Premature loss of teeth HP:0006480
Show evidence (1 reference)
PMID:39079473 SUPPORT Human Clinical
"Premature loss of teeth is an emerging finding in our cases"
Supports premature tooth loss as an emerging acatalasia manifestation.
Type 2 diabetes mellitus susceptibility
Show evidence (1 reference)
PMID:22365890 SUPPORT Other
"Inherited catalase deficiency may increase the risk of type 2 diabetes mellitus, especially for females."
Supports type 2 diabetes susceptibility as an associated phenotype.
{ }

Source YAML

click to show
name: Acatalasia
creation_date: "2026-07-06T06:09:44Z"
description: >-
  Acatalasia (acatalasemia; catalase deficiency) is a rare autosomal recessive
  disorder caused by biallelic CAT variants that reduce or abolish catalase
  activity. Catalase decomposes hydrogen peroxide to water and oxygen; deficiency
  impairs hydrogen peroxide catabolism, increases oxidative stress, and can
  present with gangrenous oral ulcerations, gangrenous periodontitis, loose
  dentition, and premature tooth loss. Published reviews also associate inherited
  catalase deficiency with increased risk of type 2 diabetes mellitus,
  especially in females, likely through chronic hydrogen peroxide/oxidative
  stress burden.
category: Metabolic Disorder
parents:
- Inborn Error of Metabolism
- Disorder of Hydrogen Peroxide Metabolism
synonyms:
- Acatalasemia
- Catalase deficiency
- CAT deficiency
- Takahara disease
classifications:
  icimd_category:
  - classification_value: intermediary_metabolism_miscellaneous
    notes: >-
      ICIMD category 13.2, other miscellaneous/unassigned disorders of
      intermediary metabolism. CAT deficiency disrupts hydrogen peroxide
      metabolism rather than glyoxylate/oxalate metabolism.
disease_term:
  preferred_term: acatalasia
  term:
    id: MONDO:0013571
    label: acatalasia
inheritance:
- name: Autosomal recessive inheritance
  inheritance_term:
    preferred_term: Autosomal recessive inheritance
    term:
      id: HP:0000007
      label: Autosomal recessive inheritance
  evidence:
  - reference: PMID:39079473
    supports: SUPPORT
    evidence_source: HUMAN_CLINICAL
    snippet: "Acatalasemia is a very rare disorder characterized by gangrenous oral ulcerations and is caused by biallelic variants in the CAT gene"
    explanation: Supports biallelic CAT variants and the recessive disease model.
pathophysiology:
- name: CAT Catalase Deficiency
  description: >-
    Biallelic CAT variants reduce catalase enzyme activity, impairing the
    conversion of hydrogen peroxide to water and oxygen.
  role: trigger
  genes:
  - preferred_term: CAT
    term:
      id: hgnc:1516
      label: CAT
  molecular_functions:
  - preferred_term: catalase activity
    term:
      id: GO:0004096
      label: catalase activity
    modifier: DECREASED
  cellular_components:
  - preferred_term: peroxisome
    term:
      id: GO:0005777
      label: peroxisome
  biological_processes:
  - preferred_term: hydrogen peroxide catabolic process
    term:
      id: GO:0042744
      label: hydrogen peroxide catabolic process
    modifier: DECREASED
  evidence:
  - reference: PMID:39079473
    supports: SUPPORT
    evidence_source: HUMAN_CLINICAL
    snippet: "biallelic variants in the CAT gene which encodes the catalase enzyme that decomposes the hydrogen peroxide molecules to remove their toxic effect."
    explanation: Supports CAT variants and catalase-mediated hydrogen peroxide decomposition.
  - reference: PMID:1999334
    supports: SUPPORT
    evidence_source: OTHER
    snippet: "in the acatalasemic gene causes a splicing mutation and hence a deficiency of mRNA."
    explanation: Historical molecular review supports catalase gene defects as the cause of acatalasemia.
  downstream:
  - target: Impaired Hydrogen Peroxide Detoxification
    causal_link_type: DIRECT
    description: Reduced catalase activity impairs hydrogen peroxide catabolism.
- name: Impaired Hydrogen Peroxide Detoxification
  description: >-
    Catalase deficiency leaves hydrogen peroxide less efficiently decomposed,
    increasing the oxidant burden on oral tissues, blood, and metabolically
    active tissues.
  role: amplifier
  biological_processes:
  - preferred_term: hydrogen peroxide catabolic process
    term:
      id: GO:0042744
      label: hydrogen peroxide catabolic process
    modifier: DECREASED
  - preferred_term: response to oxidative stress
    term:
      id: GO:0006979
      label: response to oxidative stress
    modifier: INCREASED
  chemical_entities:
  - preferred_term: hydrogen peroxide
    term:
      id: CHEBI:16240
      label: hydrogen peroxide
    modifier: INCREASED
  - preferred_term: reactive oxygen species
    term:
      id: CHEBI:26523
      label: reactive oxygen species
    modifier: INCREASED
  evidence:
  - reference: PMID:22365890
    supports: SUPPORT
    evidence_source: OTHER
    snippet: "The enzyme catalase catalyzes the breakdown of hydrogen peroxide into oxygen and water. It is the main regulator of hydrogen peroxide metabolism."
    explanation: Supports the hydrogen peroxide detoxification role of catalase.
  - reference: PMID:22365890
    supports: SUPPORT
    evidence_source: OTHER
    snippet: "Excessive concentrations may cause significant damages to protein, DNA, RNA and lipids."
    explanation: Supports oxidative macromolecular damage as the consequence of excess hydrogen peroxide.
  downstream:
  - target: Gangrenous Oral and Periodontal Tissue Injury
    causal_link_type: INDIRECT_KNOWN_INTERMEDIATES
    description: Accumulated hydrogen peroxide and oxidative stress injure oral and periodontal tissues.
  - target: Diabetes Mellitus Susceptibility
    causal_link_type: INDIRECT_UNKNOWN_INTERMEDIATES
    description: Inherited catalase deficiency has been associated with increased type 2 diabetes risk.
- name: Gangrenous Oral and Periodontal Tissue Injury
  description: >-
    Acatalasia can manifest as gangrenous oral ulcerations and periodontitis,
    with loose dentition and premature tooth loss in affected individuals.
  role: consequence
  cell_types:
  - preferred_term: gingival epithelial cell
    term:
      id: CL:0002621
      label: gingival epithelial cell
  locations:
  - preferred_term: mouth
    term:
      id: UBERON:0000165
      label: mouth
  evidence:
  - reference: PMID:39079473
    supports: SUPPORT
    evidence_source: HUMAN_CLINICAL
    snippet: "Acatalasemia is a very rare disorder characterized by gangrenous oral ulcerations"
    explanation: Supports gangrenous oral ulcerations as a core manifestation.
  - reference: PMID:39079473
    supports: SUPPORT
    evidence_source: HUMAN_CLINICAL
    snippet: "two siblings from a consanguineous Egyptian family presenting with joint hyperlaxity, loose dentitions with gangrenous periodontitis, and early loss of teeth."
    explanation: Supports periodontal injury and tooth loss in recent affected siblings.
- name: Diabetes Mellitus Susceptibility
  description: >-
    Reviews of acatalasemia and diabetes propose that inherited catalase
    deficiency can increase type 2 diabetes risk, especially in females, through
    chronic hydrogen peroxide and oxidative stress.
  role: consequence
  evidence:
  - reference: PMID:22365890
    supports: SUPPORT
    evidence_source: OTHER
    snippet: "Inherited catalase deficiency may increase the risk of type 2 diabetes mellitus, especially for females."
    explanation: Supports type 2 diabetes susceptibility as an associated downstream phenotype.
phenotypes:
- category: Clinical
  name: Gangrenous oral ulcerations
  description: Gangrenous oral ulcerations are a classic manifestation of acatalasia.
  phenotype_term:
    preferred_term: Oral ulcer
    term:
      id: HP:0000155
      label: Oral ulcer
  evidence:
  - reference: PMID:39079473
    supports: SUPPORT
    evidence_source: HUMAN_CLINICAL
    snippet: "Acatalasemia is a very rare disorder characterized by gangrenous oral ulcerations"
    explanation: Supports oral ulcerations in acatalasia.
- category: Clinical
  name: Abnormality of the gingiva
  description: Gangrenous periodontitis reflects severe gingival/periodontal tissue involvement.
  phenotype_term:
    preferred_term: Abnormality of the gingiva
    term:
      id: HP:0000168
      label: Abnormality of the gingiva
  evidence:
  - reference: PMID:39079473
    supports: SUPPORT
    evidence_source: HUMAN_CLINICAL
    snippet: "loose dentitions with gangrenous periodontitis"
    explanation: Supports gingival/periodontal involvement.
- category: Clinical
  name: Premature loss of teeth
  description: Early tooth loss was reported in affected siblings with CAT-related acatalasia.
  phenotype_term:
    preferred_term: Premature loss of teeth
    term:
      id: HP:0006480
      label: Premature loss of teeth
  evidence:
  - reference: PMID:39079473
    supports: SUPPORT
    evidence_source: HUMAN_CLINICAL
    snippet: "Premature loss of teeth is an emerging finding in our cases"
    explanation: Supports premature tooth loss as an emerging acatalasia manifestation.
- category: Clinical
  name: Type 2 diabetes mellitus susceptibility
  description: Inherited catalase deficiency has been associated with increased type 2 diabetes risk.
  evidence:
  - reference: PMID:22365890
    supports: SUPPORT
    evidence_source: OTHER
    snippet: "Inherited catalase deficiency may increase the risk of type 2 diabetes mellitus, especially for females."
    explanation: Supports type 2 diabetes susceptibility as an associated phenotype.
notes: >-
  Package seed 13.2.01.01; OMIM:614097; ORPHA:926. This entry uses the MONDO
  label "acatalasia" as the canonical disease name, with catalase deficiency and
  acatalasemia retained as synonyms.